Clinical trial • Phase III • Rare Disease
PABINAFUSP ALFA for Mucopolysaccharidosis type II | Hunter syndrome
Phase III trial of PABINAFUSP ALFA for Mucopolysaccharidosis type II | Hunter syndrome. open-label, none/not specified-controlled. 47 participants.
Overview
- Trial Therapeutic Area
- Rare Disease
- Trial Disease
- Mucopolysaccharidosis type II | Hunter syndrome
- Trial Stage
- Phase III
- Drug Modality
- Peptide/protein/enzyme
- Paediatric Trial
- Yes
- Orphan Drug
- Yes
Key dates
- Initial CTIS Submission Date
- 08-09-2023
- First CTIS Authorization Date
- 25-03-2024
Trial design
open-label, none/not specified-controlled Phase III trial in Italy, Spain, Poland and others.
- Open Label
- Yes
- Comparator
- None/Not specified
- Target Sample Size
- 47
- Trial Duration For Participant
- Cohort A: 1460 days; Cohort B: 1825 days
Eligibility
Recruits 47 paediatric patients.
- Vulnerable Population
- Vulnerable populations are explicitly considered: if the subject is aged under 18 years (under 16 years in the UK) or if willingness to participate cannot be confirmed due to MPS II–related intellectual disability, the subject’s legally acceptable representative (e.g., parents or guardians) may sign the ICF on behalf of the subject. Written informed assent should be obtained from the subject wherever possible. Country-specific assent and caregiver/parent ICF documents are provided (examples: assent documents for under/above 12 years in France, Spain, Germany, Poland, Italy). The principal investigator or designee retains original signed consent/assent documents.
Inclusion criteria
- {"criterion_text":"- A subject who participated in the Parent Study (JR-141-GS31) and completed the assessments at Week 105 in Cohort A or Week 53 in Cohort B before being administered the study medication of that respective visit, and in the opinion of the investigator, there are no safety concerns."}
- {"criterion_text":"- A subject from whom an IRB or IEC-approved written informed consent form (ICF) can be obtained, which is voluntarily signed. If the subject is aged under 18 years (aged under 16 years in the United Kingdom [UK]) at the time of enrollment or willingness to participate in the study cannot be confirmed due to MPS II related intellectual disability, the subject’s legally acceptable representative (e.g., his parents or guardians) may sign the ICF on behalf of the subject. Written informed assent should be obtained from the subject, wherever possible. The principal investigator or his/her designee will retain the original copy of each subject’s signed consent and assent (if applicable) document."}
- {"criterion_text":"- Female subject of child bearing potential or male subject whose female partner is of child-bearing potential , i.e., fertile, following menarche and until becoming post- menopausal unless permanently sterile, agrees to use a medically accepted, highly effective method of contraception, from the time of signing the ICF."}
Exclusion criteria
- {"criterion_text":"- A subject who changed treatment from JR-141 to idursulfase during the treatment period in the Parent Study (JR-141-GS31)."}
- {"criterion_text":"- A subject who is unable to comply with the protocol (e.g., is unable to return for safety evaluations or is otherwise unlikely to complete the study) as determined by the principal investigator or sub-investigator."}
- {"criterion_text":"- [Only in France] Persons deprived of their liberty by a judicial or administrative decision, according to article L. 1121-6 of the Public Health Code (Code dela santé publique, CSP) adults who are the subject of a measure of legal protection or unable to express their consent according to article L. 1121-8 of the CSP."}
Endpoints
Primary endpoints
- {"endpoint_text":"- CSF HS (Total HS and HS disaccharide), dermatan sulfate (DS), and neurofilament light chain (NfL) concentrations, and opening pressure","definition_or_measurement_approach":"Measured concentrations and opening pressure in cerebrospinal fluid (CSF); specific assays and units not detailed in the public record."}
- {"endpoint_text":"- Neuropsychological assessment","definition_or_measurement_approach":"Neuropsychological testing as per protocol (multiple standardized questionnaires and tests listed in protocol documents); exact instruments referenced in protocol questionnaires (e.g., KABC-II, WAIS/WISC/PGI scales) available in documentation."}
- {"endpoint_text":"- Others: Time course of QoL assessment, sleep disturbance, and global impression in Cohort A and Cohort B, Time course of Toileting Abilities Survey (TAS) in Cohort A and Cohort B","definition_or_measurement_approach":"Serial quality-of-life (QoL) assessments, sleep disturbance measures, global impression scales and the Toileting Abilities Survey (TAS) performed over time points in Cohorts A and B; measurement instruments referenced in protocol questionnaires."}
Secondary endpoints
- {"endpoint_text":"- Liver and spleen volume","definition_or_measurement_approach":"Organ volumes measured (likely by imaging) as per protocol; specific modality not specified in the public JSON."}
- {"endpoint_text":"- Shoulder range of motion","definition_or_measurement_approach":"Clinical assessment of shoulder range-of-motion per protocol."}
- {"endpoint_text":"- Six-minute walk test","definition_or_measurement_approach":"Standard 6-minute walk test distance measurement."}
- {"endpoint_text":"- Serum HS (Total), DS, and NfL concentrations","definition_or_measurement_approach":"Measured concentrations in serum; assay details not provided in the public JSON."}
- {"endpoint_text":"- Urinary HS (Total) and DS concentrations","definition_or_measurement_approach":"Measured concentrations in urine; assay details not provided in the public JSON."}
- {"endpoint_text":"- Pulmonary function (Cohort B only, if deemed feasible by principal investigator)","definition_or_measurement_approach":"Pulmonary function testing in Cohort B if feasible, per investigator judgment."}
- {"endpoint_text":"- Others: Time course of cardiac function (LVMI, IVST, and PWT) in Cohort A and Cohort B, Time course of T.O.V.A.® in Cohort B","definition_or_measurement_approach":"Serial cardiac function measures including LVMI, IVST, PWT and serial T.O.V.A.® testing in Cohort B as specified in protocol."}
- {"endpoint_text":"- Safety endpoints (Cohort A and Cohort B): Continuous assessment of AEs, including IARs, Periodical assessment of laboratory tests (hematology, blood biochemistry, iron-related tests, and urinalysis); vital signs (pulse rate, body temperature, respiratory rate, blood pressure); 12-lead ECG; anti-JR-141 antibodies, physical and neurological examination, weight, and height","definition_or_measurement_approach":"Continuous adverse event monitoring including infusion-related reactions (IARs); periodic laboratory testing, vital signs, 12-lead ECGs, anti-drug antibody testing, physical/neurological exams, and anthropometrics per schedule of assessments."}
Recruitment
- Planned Sample Size
- 47
- Recruitment Window Months
- 60
- Consent Approach
- Written IRB/IEC-approved informed consent (ICF) required and must be voluntarily signed. For subjects under 18 years (under 16 in the UK) or when participation willingness cannot be confirmed due to MPS II–related intellectual disability, a legally acceptable representative (e.g., parents/guardians) may sign the ICF on behalf of the subject; written informed assent should be obtained from the subject where possible. The principal investigator or designee retains the original signed consent and assent. Country-specific ICF and assent documents are provided in multiple languages (English, Spanish, French, Italian, Polish, German) as indicated by the uploaded country ICF and assent documents.
Geography
- Total Number Of Sites
- 12
- Total Number Of Participants
- 32
Italy
- Earliest CTIS Part Ii Submission Date
- 10-07-2024
- Latest Decision Or Authorization Date
- 31-07-2024
- Processing Time Days
- 21
- Number Of Sites
- 2
- Number Of Participants
- 4
Sites
- Site Name
- Ospedale Pediatrico Bambino Gesu
- Department Name
- 901:Child Neuorology, U.O.C Malattie Metaboliche ed Epatologia
- Contact Person Name
- Federica Deodato
- Contact Person Email
- federica.deodato@opbg.net
- Site Name
- Fondazione IRCCS San Gerardo Dei Tintori
- Department Name
- 902:Centro malattie Metaboliche, Dipartimento Pediatria
- Contact Person Name
- Serena Gasperini
- Contact Person Email
- serena.gasperini@irccs-sangerardo.it
Spain
- Earliest CTIS Part Ii Submission Date
- 12-03-2024
- Latest Decision Or Authorization Date
- 25-03-2024
- Processing Time Days
- 13
- Number Of Sites
- 2
- Number Of Participants
- 5
Sites
- Site Name
- University Hospital Virgen Del Rocio S.L.
- Department Name
- 603:Neurocirugía Infantil y General
- Contact Person Name
- Antonio Gonzalez Meneses
- Contact Person Email
- Antonio.gonzalezmeneses.l.sspa@juntadeandalucia.es
- Site Name
- Sant Joan De Deu Barcelona Hospital
- Department Name
- 602:Neurología Pediátrica
- Contact Person Name
- Leticia Pias Peleteiro
- Contact Person Email
- leticiadiana.pias@sjd.es
Poland
- Earliest CTIS Part Ii Submission Date
- 15-03-2024
- Latest Decision Or Authorization Date
- 02-04-2024
- Processing Time Days
- 18
- Number Of Sites
- 1
- Number Of Participants
- 6
Sites
- Site Name
- Uniwersytecki Szpital Dzieciecy W Krakowie
- Department Name
- 801:Oddzial Pediatrii, Reumatologii i Chorob Rzadkich
- Contact Person Name
- Przemko Kwinta
- Contact Person Email
- przemko.kwinta@uj.edu.pl
France
- Earliest CTIS Part Ii Submission Date
- 12-04-2024
- Latest Decision Or Authorization Date
- 16-04-2024
- Processing Time Days
- 4
- Number Of Sites
- 3
- Number Of Participants
- 10
Sites
- Site Name
- Hospices Civils De Lyon
- Department Name
- 201: Chirurgie uro-génitale, viscér
- Contact Person Name
- Nathalie GUFFON
- Contact Person Email
- nathalie.guffon-fouilhoux@chu-lyon.fr
- Site Name
- Centre Hospitalier Universitaire De Montpellier
- Department Name
- 203:Neuropédiatrie
- Contact Person Name
- Agathe Roubertie
- Contact Person Email
- a-roubertie@chu-montpellier.fr
- Site Name
- Trousseau Hospital
- Department Name
- 202:Service Neuropédiatrie et Path
- Contact Person Name
- Benedicte HERON
- Contact Person Email
- benedicte.heron@trs.aphp.fr
Germany
- Earliest CTIS Part Ii Submission Date
- 12-03-2024
- Latest Decision Or Authorization Date
- 03-04-2024
- Processing Time Days
- 22
- Number Of Sites
- 4
- Number Of Participants
- 7
Sites
- Site Name
- Universitaetsklinikum Giessen und Marburg GmbH
- Department Name
- 104:Pneumology
- Contact Person Name
- Christina Lampe
- Contact Person Email
- Christina.Lampe@paediat.med.uni-giessen.de
- Site Name
- University Medical Center Hamburg-Eppendorf
- Department Name
- 101:Kinder- und Jugendmedizin
- Contact Person Name
- Nicole Muschol
- Contact Person Email
- muschol@uke.uni-hamburg.de
- Site Name
- SphinCS GmbH
- Department Name
- 102:
- Contact Person Name
- Eugen Mengel
- Contact Person Email
- eugen.mengel@sphincs.de
- Site Name
- Universitaetsmedizin der Johannes Gutenberg-Universitaet Mainz KöR
- Department Name
- 103: Zentrum für Kinder- und Jugendmedizin
- Contact Person Name
- Julia Hennermann
- Contact Person Email
- julia.hennermann@unimedizin-mainz.de
Sponsor
Primary sponsor
- Full Name
- Jcr Pharmaceuticals Co. Ltd.
- Organisation Type
- Pharmaceutical company
- Country Of Registered Address
- Japan
Contract research organisations
- Name
- PPD Global Limited
- Responsibilities
- sponsorDuties codes: 9
- Name
- Parexel International (IRL) Limited
- Responsibilities
- sponsorDuties codes: 1, 12, 13, 2, 5
- Name
- Statistics & Data Corp.
- Responsibilities
- sponsorDuties codes: 10, 6, 7
- Name
- Medidata Solutions Inc.
- Responsibilities
- sponsorDuties code: 7
- Name
- Eresearchtechnology Inc.
- Responsibilities
- Neurocognitive assessment training and review
Third parties
- {"country":"United States","full_name":"Scout Clinical","duties_or_roles":"Subject and caregiver travel bookings and reimbursements","organisation_type":"Hospital/Clinic/Other health care facility"}
- {"country":"United Kingdom","full_name":"PPD Global Limited","duties_or_roles":"sponsorDuties codes: 9","organisation_type":"Pharmaceutical company"}
- {"country":"United Kingdom","full_name":"Primevigilance Limited","duties_or_roles":"sponsorDuties code: 8","organisation_type":"Pharmaceutical company"}
- {"country":"Japan","full_name":"Shin Nippon Biomedical Laboratories Ltd.","duties_or_roles":"Antibody testing; sponsorDuties code: 4","organisation_type":"Industry"}
- {"country":"United States","full_name":"Eresearchtechnology Inc.","duties_or_roles":"Neurocognitive assessment training and review","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Medidata Solutions Inc.","duties_or_roles":"sponsorDuties code: 7","organisation_type":"Non-Pharmaceutical company"}
- {"country":"Japan","full_name":"EPS Corporation","duties_or_roles":"sponsorDuties code: 3","organisation_type":"Industry"}
- {"country":"United States","full_name":"Statistics & Data Corp.","duties_or_roles":"sponsorDuties codes: 10, 6, 7","organisation_type":"Pharmaceutical company"}
- {"country":"United Kingdom","full_name":"Medical Research Network Limited","duties_or_roles":"home trial support provider","organisation_type":"Laboratory/Research/Testing facility"}
- {"country":"United States","full_name":"Duke University Health System (DUHS) Clinical Laboratories","duties_or_roles":"CRIM status","organisation_type":"Industry"}
- {"country":"Ireland","full_name":"Parexel International (IRL) Limited","duties_or_roles":"sponsorDuties codes: 1, 12, 13, 2, 5","organisation_type":"Pharmaceutical company"}
- {"country":"Japan","full_name":"Micron Inc.","duties_or_roles":"Medical image analysis/review - X-ray, MRI, ultrasound, etc.","organisation_type":"Pharmaceutical company"}
- {"country":"Japan","full_name":"Shin Nippon Biomedical Laboratories Ltd.","duties_or_roles":"sponsorDuties code: 4","organisation_type":"Pharmaceutical company"}
- {"country":"Japan","full_name":"Advanced Medical Laboratory of National Center for Child Health and Development","duties_or_roles":"Gene testing","organisation_type":"Industry"}
- {"country":"United States","full_name":"Frontage Laboratories Inc.","duties_or_roles":"sponsorDuties code: 4","organisation_type":"Pharmaceutical company"}
Investigational products
- Investigational Product Name
- JR-141
- Active Substance
- PABINAFUSP ALFA
- Modality
- Peptide/protein/enzyme
- Routes Of Administration
- INTRAVENOUS INJECTION
- Route
- INTRAVENOUS INJECTION
- Authorisation Status
- prodAuthStatus 1
- Orphan Designation
- Yes
- Maximum Dose
- 2.0 mg/kg
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