Clinical trial • Phase II/III • Rare Disease
BMN 333 for Achondroplasia
Phase II/III trial of BMN 333 for Achondroplasia.
Overview
- Trial Therapeutic Area
- Rare Disease
- Trial Disease
- Achondroplasia
- Trial Stage
- Phase II/III
- Drug Modality
- Peptide/protein/enzyme
- Paediatric Trial
- Yes
- Orphan Drug
- Yes
Key dates
- Initial CTIS Submission Date
- 19-02-2026
- First CTIS Authorization Date
- 05-05-2026
Trial design
Randomised, open-label, vosoritide (voxzogo) — subcutaneous (sc) once daily, weight‑band dosing (protocol references voxzogo 0.56 mg and voxzogo 1.2 mg presentations).-controlled, adaptive Phase II/III trial across 7 sites in Italy, Romania, Poland.
- Randomised
- Yes
- Open Label
- Yes
- Comparator
- Vosoritide (Voxzogo) — subcutaneous (SC) once daily, weight‑band dosing (protocol references Voxzogo 0.56 mg and Voxzogo 1.2 mg presentations).
- Adaptive
- True, interim analysis planned after all Phase 2 participants complete 26 weeks or discontinue earlier; unblinded review of efficacy, safety and available PK data to select Phase 3 dose and decide whether to proceed to Phase 3 (operationally seamless Phase 2/3 design).
- Single Multiple Or Escalation Dose Combined
- Yes
- Target Sample Size
- 160
- Trial Duration For Participant
- 427
Stratification factors
- Sex
- Age group (≥5 years vs <5 years) - Phase 2
- Tanner stage - Phase 3
Eligibility
Recruits 160 paediatric patients.
- Pregnancy Exclusion
- 3.Females ≥ 10 years old or who have begun menses must have a negative pregnancy test at the Screening visit and be willing to have additional pregnancy tests during the study.
- Vulnerable Population
- Participants are children (paediatric population) aged from ≥2 to <11 years (Phase 2) and ≥2 to <18 years (Phase 3). Vulnerable-population procedures are in place: parent/guardian consent and age-appropriate assent forms are provided (documents include assent forms for younger children and older children/adolescents). Multiple site-specific ICF and assent documents are provided (examples in Italian, Polish, Romanian). Caregivers are required to be willing to administer injections and complete required training.
Inclusion criteria
- {"criterion_text":"- 1.Participants must be aged ≥ 2 to < 11 years (Phase 2) or ≥ 2 to < 18 years (Phase 3), at the time of signing the informed consent.\n- 2.Participants must have ACH (confirmed by documented genetic testing) and open epiphyses assessed using left hand postero-anterior (PA) X-rays, by the Greulich and Pyle method (Greulich 1971) as per standard of care.\n- 3.Females ≥ 10 years old or who have begun menses must have a negative pregnancy test at the Screening visit and be willing to have additional pregnancy tests during the study.\n- 4.Are Tanner Stage I (Phase 2) or any Tanner stage (Phase 3)\n- 5.Have a body weight ≥ 8.0 kg at the Screening visit\n- 6.Are ambulatory and able to stand without assistance\n- 7.Caregivers are willing to administer injections to the participants and willing to complete the required training."}
Exclusion criteria
- {"criterion_text":"- 1.Have any short stature condition other than ACH (eg, hypochondroplasia, trisomy 21, pseudoachondroplasia, GH deficiency).\n- 2.Have any of the following disorders:Hypothyroidism or hyperthyroidism (unless treated) ,Diabetes mellitus (unless considered well-controlled), Autoimmune inflammatory disease, Autoimmune inflammatory disease ,Autonomic neuropathy.\n- 3.Have history of: Renal insufficiency, Cardiac or vascular disease, unstable clinical condition , significant hip pathology."}
Endpoints
Primary endpoints
- {"endpoint_text":"- Phase 2: Predicted AGV at Week 52 (based on AGV at Weeks 26, 39, and 52 [available cumulative data])","definition_or_measurement_approach":"Predicted annualized growth velocity (AGV) at Week 52 estimated based on observed AGV at Weeks 26, 39 and 52 (cumulative data available for interim assessments)."}
- {"endpoint_text":"- Phase 3: AGV at Week 52","definition_or_measurement_approach":"Annualized growth velocity (AGV) measured at Week 52."}
Secondary endpoints
- {"endpoint_text":"- Phase 2: 1.AGV at Weeks 26 and 52 2.Change from Baseline in standing height, height Z-score and in upper to lower body segment ratio at Weeks 26 and 52 3.Incidence of AEs, SAEs, and EOIsa; physical examinations; vital signs; ECG findings; imaging results (X-ray and DXA); clinical laboratory tests.","definition_or_measurement_approach":"AGV measured at Weeks 26 and 52; standing height, height Z-score and upper/lower body segment ratio changes from baseline at Weeks 26 and 52; safety measured by incidence of adverse events, serious adverse events and events of special interest, plus physical exams, vital signs, ECG, imaging (X-ray and DXA) and clinical laboratory tests."}
- {"endpoint_text":"- Phase 3: • Change from Baseline in standing height, height Z-score, upper to lower body segment ratio at Week 52","definition_or_measurement_approach":"Change from baseline in standing height, height Z-score and upper to lower body segment ratio measured at Week 52."}
Recruitment
- Planned Sample Size
- 160
- Recruitment Window Months
- 37
- Consent Approach
- Informed consent is obtained from parents/legal guardians. Age-appropriate assent is obtained from children using specific assent documents (examples: Assent 6-11, Assent 12-17, Young Child Assent, Older Child Assent). Site-specific subject information and informed consent forms and assent forms are provided in multiple languages (document list includes Italian, Polish and Romanian versions). Parent/guardian ICFs and optional research consent forms are included for each country/site.
Methods
- Site-based recruitment at participating hospitals/clinical sites in the listed countries (Italy, Romania, Poland) — recruitment through the trial sites named in Part II submissions.
- Provision of patient recruitment materials managed by ICON Clinical Research Limited (duty listed: 'Patient recruitement Materials').
- Patient reimbursement handled by Scout Clinical (duty listed: 'Patient reimbursement').
Geography
- Total Number Of Sites
- 7
- Total Number Of Participants
- 25
Italy
- Earliest CTIS Part Ii Submission Date
- 10-04-2026
- Latest Decision Or Authorization Date
- 05-05-2026
- Processing Time Days
- 25
- Number Of Sites
- 3
- Number Of Participants
- 15
Sites
- Site Name
- IRCCS Istituto Giannina Gaslini
- Department Name
- Pediatric Clinic - Clinical Service in Pediatric Endocrinology, Diabetes and Metabolism
- Contact Person Name
- Mohamad Maghnie
- Contact Person Email
- mohamadmaghnie@gaslini.org
- Site Name
- Fondazione Policlinico Universitario Agostino Gemelli IRCCS
- Department Name
- UOC Pediatrics
- Contact Person Name
- Roberta Onesimo
- Contact Person Email
- roberta.onesimo@policlinicogemelli.it
- Site Name
- Fondazione IRCCS Ca Granda Ospedale Maggiore Policlinico
- Department Name
- Maternal and Childhood Area
- Contact Person Name
- Maria Francesca Bedeschi
- Contact Person Email
- mariafrancesca.bedeschi@policlinico.mi.it
Romania
- Earliest CTIS Part Ii Submission Date
- 14-04-2026
- Latest Decision Or Authorization Date
- 05-05-2026
- Processing Time Days
- 21
- Number Of Sites
- 2
- Number Of Participants
- 5
Sites
- Site Name
- National Institute Of Endocrinology C.I. Parhon
- Department Name
- Endocrinology
- Contact Person Name
- Iuliana Gherlan
- Contact Person Email
- contact@parhon.ro
- Site Name
- Spitalul Clinic Judetean De Urgenta Craiova
- Department Name
- Genetics
- Contact Person Name
- Ioana Streata
- Contact Person Email
- info@scjuc.ro
Poland
- Earliest CTIS Part Ii Submission Date
- 13-04-2026
- Latest Decision Or Authorization Date
- 05-05-2026
- Processing Time Days
- 22
- Number Of Sites
- 2
- Number Of Participants
- 5
Sites
- Site Name
- Uniwersytecki Szpital Kliniczny Im. Jana Mikulicza-Radeckiego We Wroclawiu
- Department Name
- Klinika Pediatrii, Endokrynologii, Diabetologii i Chorób Metabolicznych
- Contact Person Name
- Robert Śmigiel
- Contact Person Email
- robert.smigiel@umw.edu.pl
- Site Name
- Samodzielny Publiczny Szpital Kliniczny Nr 1 Im.Prof.Stanislawa Szyszko Slaskiego Uniwersytetu Medycznego W Katowicach
- Department Name
- Poradnia Endokrynologii Dziecięcej
- Contact Person Name
- Agnieszka Zachurzok
- Contact Person Email
- azachurzok@sum.edu.pl
Sponsor
Primary sponsor
- Full Name
- Biomarin Pharmaceutical Inc.
- Organisation Type
- Pharmaceutical company
- Country Of Registered Address
- United States
Contract research organisations
- Name
- Medpace Belgium
- Name
- Icon Clinical Research Limited
- Responsibilities
- Site and contract negotiation, Medical Imaging, In-home health, language services, Patient recruitement Materials.
- Name
- Imperial Clinical Research Services International Ltd.
- Responsibilities
- printing
- Name
- Medpace Singapore Pte Ltd
- Name
- Medpace Reference Laboratories LLC
Third parties
- {"country":"Belgium","full_name":"Medpace Belgium","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"France","full_name":"Sysnav","duties_or_roles":"Digital Health Technologies (DHT)","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Medpace Reference Laboratories LLC","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Bioagilytix Labs LLC","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Azenta US Inc.","duties_or_roles":"long term storage","organisation_type":"Pharmaceutical company"}
- {"country":"United Kingdom","full_name":"ATOM International Limited","duties_or_roles":"Antropometric Measurement training","organisation_type":"Non-Pharmaceutical company"}
- {"country":"Germany","full_name":"Centogene GmbH","duties_or_roles":"","organisation_type":"Laboratory/Research/Testing facility"}
- {"country":"United States","full_name":"Yprime LLC","duties_or_roles":"","organisation_type":"Non-Pharmaceutical company"}
- {"country":"United States","full_name":"Alliance Pharma Inc.","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"United Kingdom","full_name":"Woodley Equipment Company Limited","duties_or_roles":"Anthropometric Equipment","organisation_type":"Pharmaceutical company"}
- {"country":"France","full_name":"Quipment","duties_or_roles":"Equipmental Rental","organisation_type":"Non-Pharmaceutical company"}
- {"country":"United States","full_name":"Imperial Clinical Research Services International Ltd.","duties_or_roles":"printing","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Azenta US Inc.","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"Singapore","full_name":"Medpace Singapore Pte Ltd","duties_or_roles":"","organisation_type":"Pharmaceutical company"}
- {"country":"United States","full_name":"Medidata Solutions Inc.","duties_or_roles":"","organisation_type":"Non-Pharmaceutical company"}
- {"country":"United States","full_name":"Suvoda LLC","duties_or_roles":"","organisation_type":"Non-Pharmaceutical company"}
- {"country":"United States","full_name":"Scout Clinical","duties_or_roles":"Patient reimbursement","organisation_type":"Hospital/Clinic/Other health care facility"}
- {"country":"Ireland","full_name":"Icon Clinical Research Limited","duties_or_roles":"Site and contract negotiation, Medical Imaging, In-home health, language services, Patient recruitement Materials.","organisation_type":"Pharmaceutical company"}
Investigational products
- Investigational Product Name
- BMN 333
- Active Substance
- BMN 333
- Modality
- Peptide/protein/enzyme
- Routes Of Administration
- SUBCUTANEOUS USE
- Route
- Subcutaneous
- Authorisation Status
- prodAuthStatus: 1 (not marketing authorised / development product)
- Dose Levels
- Three weekly dose levels (Dose A, Dose B, Dose C) described in Phase 2; specific numeric doses not stated in CTIS data
- Frequency
- Once weekly (protocol: BMN 333 once weekly in Phase 2 and selected once-weekly dose in Phase 3)
- Dose Escalation Increase
- Dose A, Dose B, Dose C (specific increases not stated in CTIS data)
- Investigational Product Name
- Voxzogo 0.56 mg powder and solvent for solution for injection
- Active Substance
- VOSORITIDE
- Modality
- Peptide/protein/enzyme
- Routes Of Administration
- SUBCUTANEOUS USE
- Route
- Subcutaneous
- Authorisation Status
- Authorised (marketingAuthNumber: EU/1/21/1577/002)
- Orphan Designation
- Yes
- Dose Levels
- Weight-band daily dosing as per protocol (specific weight-band doses not provided in CTIS data); product strength 0.56 mg referenced
- Frequency
- Once daily (weight-band dosing)
- Maximum Dose
- 0.40 mg (maxDailyDoseAmount field in CTIS record)
- Investigational Product Name
- Voxzogo 1.2 mg powder and solvent for solution for injection
- Active Substance
- VOSORITIDE
- Modality
- Peptide/protein/enzyme
- Routes Of Administration
- SUBCUTANEOUS USE
- Route
- Subcutaneous
- Authorisation Status
- Authorised (marketingAuthNumber: EU/1/21/1577/003)
- Orphan Designation
- Yes
- Dose Levels
- Weight-band daily dosing as per protocol (specific weight-band doses not provided in CTIS data); product strength 1.2 mg referenced
- Frequency
- Once daily (weight-band dosing)
- Maximum Dose
- 0.80 mg (maxDailyDoseAmount field in CTIS record)
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