Clinical trial • Phase III • Neurology|Rare Disease

ONASEMNOGENE ABEPARVOVEC for Spinal muscular atrophy

Phase III trial of ONASEMNOGENE ABEPARVOVEC for Spinal muscular atrophy. open-label, none/not specified-controlled. 147 participants.

Overview

Trial Therapeutic Area
Neurology|Rare Disease
Trial Disease
Spinal muscular atrophy
Trial Stage
Phase III
Drug Modality
Gene therapy
Paediatric Trial
Yes
Orphan Drug
Yes

Key dates

Initial CTIS Submission Date
10-07-2024
First CTIS Authorization Date
08-08-2024

Trial design

open-label, none/not specified-controlled Phase III trial in Belgium, Denmark, France and others.

Open Label
Yes
Comparator
None/Not specified
Target Sample Size
147
Trial Duration For Participant
1825

Eligibility

Recruits 147 paediatric patients.

Vulnerable Population
Vulnerable population: minors/children. The trial selects vulnerable populations (isVulnerablePopulationSelected = true). Written informed consent is required prior to any assessments and must be provided by the patient or the patient’s parent/legal guardian. Assent forms and caregiver/parent information sheets are provided for minors (country-specific assent/I CF documents listed for ages including 7-11 and 12-17; Denmark has assent documents for 12-14 and 15-17). Country-specific caregiver/parent ICFs and child/adolescent assent forms are included in the documentation.

Inclusion criteria

  • {"criterion_text":"- Participated in an OAV101 clinical trial.\n- Written informed consent must be obtained before any assessment is performed.\n- Patient/Parent/legal guardian willing and able to comply with study procedures."}

Exclusion criteria

  • {"criterion_text":"- There are no specific exclusion criteria for this study."}

Endpoints

Primary endpoints

  • {"endpoint_text":"- Number and proportion of patients reporting treatment-emergent serious adverse events (SAEs) by Medical Dictionary for Regulatory Activities (MedDRA) System Organ Class (SOC) and Preferred Term (PT) for the entire duration of the study (i.e., up to 5 years)","definition_or_measurement_approach":"SAEs will be summarised by MedDRA System Organ Class (SOC) and Preferred Term (PT) for the entire study duration (up to 5 years)."}
  • {"endpoint_text":"- Number and proportion of patients reporting treatment-emergent adverse events of special interest (AESIs) by AESI category and MedDRA SOC and PT within each AESI category for the entire duration of the study (i.e., up to 5 years)","definition_or_measurement_approach":"AESIs will be categorised by AESI category and summarised by MedDRA SOC and PT within each AESI category for the entire study duration (up to 5 years)."}

Secondary endpoints

  • {"endpoint_text":"- The number and proportion of participants demonstrating each developmental milestone according to the Developmental Milestone Checklist","definition_or_measurement_approach":"Count and proportion reaching each milestone as per the Developmental Milestone Checklist."}
  • {"endpoint_text":"- The number and proportion of participants demonstrating maintenance of each developmental milestone","definition_or_measurement_approach":"Count and proportion demonstrating maintenance of each developmental milestone (method: checklist comparison to prior status)."}
  • {"endpoint_text":"- Change from Baseline in the Hammersmith Functional Motor Scale – Expanded (HFMSE) total score","definition_or_measurement_approach":"Change from baseline in total HFMSE score."}
  • {"endpoint_text":"- Change from Baseline in the Revised Upper Limb Module (RULM) total score","definition_or_measurement_approach":"Change from baseline in total RULM score."}
  • {"endpoint_text":"- Number and proportion of patients with potentially clinically significant vital sign findings, summarized individually for each vital sign parameter","definition_or_measurement_approach":"Number and proportion with clinically significant abnormal vital sign findings, summarized by each vital sign parameter."}
  • {"endpoint_text":"- Number and proportion of patients with potentially clinically significant laboratory values, summarized individually for each laboratory parameter","definition_or_measurement_approach":"Number and proportion with clinically significant laboratory abnormalities, summarized by each laboratory parameter."}

Recruitment

Planned Sample Size
147
Recruitment Window Months
92
Consent Approach
Written informed consent must be obtained before any assessment. Consent may be provided by the patient or by the parent/legal guardian where applicable. Assent is used for minors: country-specific assent documents are provided (examples in the documentation include assent forms for ages 7-11 and 12-17 in Belgium; assent forms for 12-14 and 15-17 in Denmark; child and adolescent assent in Italy; assent documents in the Netherlands). Caregiver/parent information sheets and caregiver consent forms are provided. Country-specific ICF and assent documents are available in the listed country languages.

Geography

Total Number Of Sites
9
Total Number Of Participants
26

Belgium

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
08-08-2024
Processing Time Days
42
Number Of Sites
1
Number Of Participants
4

Sites

Site Name
UZ Leuven
Department Name
1201: Pediatric neurology
Principal Investigator Name
Liesbeth De Waele
Principal Investigator Email
liesbeth.dewaele@uzleuven.be
Contact Person Name
Liesbeth De Waele
Contact Person Email
liesbeth.dewaele@uzleuven.be
Number Of Participants
4

Denmark

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
13-08-2024
Processing Time Days
47
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Rigshospitalet
Department Name
1701: Hematology
Principal Investigator Name
Alfred Peter Born
Principal Investigator Email
alfred.peter.born@regionh.dk
Contact Person Name
Alfred Peter Born
Contact Person Email
alfred.peter.born@regionh.dk
Number Of Participants
3

France

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
20-08-2024
Processing Time Days
54
Number Of Sites
4
Number Of Participants
7

Sites

Site Name
Les Hopitaux Universitaires De Strasbourg
Department Name
1902: Département de Pédiatrie
Principal Investigator Name
Vincent Laugel
Principal Investigator Email
vincent.laugel@chru-strasbourg.fr
Contact Person Name
Vincent Laugel
Number Of Participants
7
Site Name
Raymond-Poincare Hospital
Department Name
1901: Unité Neuromusculaire, Département de Neurologie pédiatrique et Unité de Soins Intensifs
Principal Investigator Name
Susana Quijano-Roy
Principal Investigator Email
susana.quijano-roy@aphp.fr
Contact Person Name
Susana Quijano-Roy
Contact Person Email
susana.quijano-roy@aphp.fr
Site Name
Hospital Femme Mere Enfant
Department Name
1903: Service MPR pédiatrique L'Escale
Principal Investigator Name
Laure Le Goff
Principal Investigator Email
laure.le-goff@chu-lyon.fr
Contact Person Name
Laure Le Goff
Contact Person Email
laure.le-goff@chu-lyon.fr
Site Name
Hopital Des Enfants
Department Name
1904: Neurologie pédiatrique
Principal Investigator Name
Claude Cancès
Principal Investigator Email
cances.c@chu-toulouse.fr
Contact Person Name
Claude Cancès
Contact Person Email
cances.c@chu-toulouse.fr

Italy

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
17-09-2024
Processing Time Days
82
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Universita Cattolica Del Sacro Cuore
Department Name
2201: Pediatric neurology
Principal Investigator Name
Eugenio Mercuri
Principal Investigator Email
eugeniomaria.mercuri@policlinicogemelli.it
Contact Person Name
Eugenio Mercuri
Number Of Participants
3

Spain

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
26-08-2024
Processing Time Days
60
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Hospital Universitari Vall D Hebron
Department Name
3201: Pediatric Neurology
Principal Investigator Name
Francina Munell Casadesus
Principal Investigator Email
francina.munell@vhir.org
Contact Person Name
Francina Munell Casadesus
Contact Person Email
francina.munell@vhir.org
Number Of Participants
3

Netherlands

Earliest CTIS Part Ii Submission Date
27-06-2024
Latest Decision Or Authorization Date
12-08-2024
Processing Time Days
46
Number Of Sites
1
Number Of Participants
6

Sites

Site Name
Universitair Medisch Centrum Utrecht
Department Name
2601: Sylvia Toth Centrum
Principal Investigator Name
W.L. (Ludo) van der Pol
Principal Investigator Email
W.L.vanderPol@umcutrecht.nl
Contact Person Name
W.L. (Ludo) van der Pol
Contact Person Email
W.L.vanderPol@umcutrecht.nl
Number Of Participants
6

Sponsor

Primary sponsor

Full Name
Novartis Pharma AG
Organisation Type
Pharmaceutical company
Country Of Registered Address
Switzerland

Contract research organisations

Name
Parexel International (IRL) Limited
Responsibilities
Study Start-Up (including site contracts and Ethics committee submissions) Site Management; duties codes:1,10,11,12,15,5,6,7,8
Name
Q Squared Solutions Holdings LLC
Responsibilities
code:4
Name
Q Squared Solutions Limited
Responsibilities
code:4
Name
Labcorp Early Development Laboratories Inc.
Responsibilities
code:4
Name
Bioagilytix Labs LLC
Responsibilities
code:4
Name
Eresearchtechnology Inc.
Responsibilities
PRO management, PRO licensing and translations, data collection via tablet, Site Training for clinical evaluators.
Name
SGS France
Responsibilities
code:4

Third parties

  • {"country":"Germany","full_name":"ProtaGene CGT GmbH","duties_or_roles":"code:4","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Q Squared Solutions Holdings LLC","duties_or_roles":"code:4","organisation_type":"Laboratory/Research/Testing facility"}
  • {"country":"United States","full_name":"Transperfect Translations International Inc.","duties_or_roles":"Translation and licensing","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Labcorp Early Development Laboratories Inc.","duties_or_roles":"code:4","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Greenphire LLC","duties_or_roles":"Transport/ Concierge services for patients","organisation_type":"Non-Pharmaceutical company"}
  • {"country":"United Kingdom","full_name":"Q Squared Solutions Limited","duties_or_roles":"code:4","organisation_type":"Non-Pharmaceutical company"}
  • {"country":"United States","full_name":"Bioagilytix Labs LLC","duties_or_roles":"code:4","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Ancillare LP","duties_or_roles":"Ordering, storage and distribution of RULM kits","organisation_type":"Pharmaceutical company"}
  • {"country":"Ireland","full_name":"Parexel International (IRL) Limited","duties_or_roles":"codes:1,10,11,12,15,5,6,7,8; Study Start-Up (including site contracts and Ethics committee submissions) Site Management","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Eresearchtechnology Inc.","duties_or_roles":"PRO management, PRO licensing and translations, data collection via tablet, Site Training for clinical evaluators.","organisation_type":"Pharmaceutical company"}
  • {"country":"France","full_name":"SGS France","duties_or_roles":"code:4","organisation_type":"Pharmaceutical company"}

Investigational products

Investigational Product Name
OAV101B
Active Substance
ONASEMNOGENE ABEPARVOVEC
Modality
Gene therapy
Routes Of Administration
Intrathecal
Route
Intrathecal
Orphan Designation
Yes
Investigational Product Name
Zolgensma 2 × 10^13 vector genomes/mL solution for infusion
Active Substance
ONASEMNOGENE ABEPARVOVEC
Modality
Gene therapy
Routes Of Administration
Intravenous
Route
Intravenous
Authorisation Status
Authorised (EU marketing authorisation EU/1/20/1443/001)
Orphan Designation
Yes

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