Clinical trial • Phase II • Rare Disease|Haematology

HUMAN APOTRANSFERRIN for Congenital atransferrinaemia|Hypotransferrinaemia

Phase II trial of HUMAN APOTRANSFERRIN for Congenital atransferrinaemia|Hypotransferrinaemia. open-label, adaptive. 5 participants.

Overview

Trial Therapeutic Area
Rare Disease|Haematology
Trial Disease
Congenital atransferrinaemia|Hypotransferrinaemia
Trial Stage
Phase II
Drug Modality
Peptide/protein/enzyme
Paediatric Trial
Yes
Orphan Drug
Yes

Key dates

Initial CTIS Submission Date
15-07-2024
First CTIS Authorization Date
02-08-2024

Trial design

open-label, adaptive Phase II trial across 3 sites in Germany, Spain, Italy.

Open Label
Yes
Adaptive
Yes
Single Multiple Or Escalation Dose Combined
Yes
Target Sample Size
5
Trial Duration For Participant
756

Eligibility

Recruits 5 paediatric patients.

Pregnancy Exclusion
Fertile women unless they take valid contraceptive measures (ITA only)
Vulnerable Population
Children are included as a vulnerable population. Subject information and informed consent forms are available for children (including a child ICF for ages 7-12) and for parents; parental consent/parent information forms are provided. Signed informed consent is required.

Inclusion criteria

  • {"criterion_text":"- Established diagnosis of atransferrinemia, defined as serum levels of transferrin below 40 mg/dL"}
  • {"criterion_text":"- Signed informed consent"}

Exclusion criteria

  • {"criterion_text":"- Known with allergic reactions against human plasma or plasma products"}
  • {"criterion_text":"- Having detectable anti-IgA antibodies"}
  • {"criterion_text":"- Fertile women unless they take valid contraceptive measures (ITA only)"}

Endpoints

Primary endpoints

  • {"endpoint_text":"- Increase of hemoglobin (to normal range)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Pharmacokinetics of transferrin","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Decrease of serum ferritin (to normal range)","definition_or_measurement_approach":""}

Secondary endpoints

  • {"endpoint_text":"- Increase of hematocrit (to normal range)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Increase of erythrocytes (to normal range)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Decrease of iron overload (liver, heart)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Transferrin levels, transferrin saturation, and serum iron in relation to efficacy","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Undetectable NTBI/LPI levels","definition_or_measurement_approach":""}

Recruitment

Planned Sample Size
5
Recruitment Window Months
210
Consent Approach
Signed informed consent is required. Subject information and informed consent forms exist for adults and children, including a child ICF for ages 7-12 and parental consent/information forms. Documents are available in multiple languages (DE, ES, IT, EN versions present). Parental consent is used for minors; child-specific ICFs are provided.

Geography

Total Number Of Sites
3
Total Number Of Participants
5

Germany

Earliest CTIS Part Ii Submission Date
01-08-2024
Latest Decision Or Authorization Date
12-01-2026
Processing Time Days
529
Number Of Sites
1
Number Of Participants
2

Sites

Site Name
Klinikum Aschaffenburg-Alzenau gGmbH
Department Name
Klinik für Kinder- und Jugendmedizin
Principal Investigator Name
Katja Moser
Principal Investigator Email
Katja.Moser@klinikum-ab-alz.de
Contact Person Name
Katja Moser
Contact Person Email
Katja.Moser@klinikum-ab-alz.de
Number Of Participants
2

Spain

Earliest CTIS Part Ii Submission Date
01-08-2024
Latest Decision Or Authorization Date
20-01-2026
Processing Time Days
537
Number Of Sites
1
Number Of Participants
2

Sites

Site Name
Hospital Universitari Vall D Hebron
Department Name
Area Materno-Infantil
Principal Investigator Name
Cristina Diaz de Heredia Rubio
Principal Investigator Email
cristina.diazdeheredia@vallhebron.cat
Contact Person Name
Cristina Diaz de Heredia Rubio
Number Of Participants
2

Italy

Earliest CTIS Part Ii Submission Date
01-08-2024
Latest Decision Or Authorization Date
20-01-2026
Processing Time Days
537
Number Of Sites
1
Number Of Participants
1

Sites

Site Name
Fondazione IRCCS San Gerardo Dei Tintori
Department Name
SSD Malattie Rare
Principal Investigator Name
Raffaella Mariani
Principal Investigator Email
r.mariani@asst-monza.it
Contact Person Name
Raffaella Mariani
Contact Person Email
r.mariani@asst-monza.it
Number Of Participants
1

Sponsor

Primary sponsor

Full Name
Prothya Biosolutions Netherlands B.V.
Organisation Type
Pharmaceutical company
Country Of Registered Address
Netherlands

Investigational products

Investigational Product Name
Human Apotransferrin (50g/l)
Active Substance
HUMAN APOTRANSFERRIN
Modality
Peptide/protein/enzyme
Routes Of Administration
Intravenous infusion
Route
Intravenous infusion
Orphan Designation
Yes
Frequency
Every 4-8 weeks
Maximum Dose
360 mg/kg (max daily); 30 mg (max total)

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