Clinical trial • Phase II/III • Haematology|Rare Disease

ETRANACOGENE DEZAPARVOVEC for Hemophilia B

Phase II/III trial of ETRANACOGENE DEZAPARVOVEC for Hemophilia B. open-label, none/not specified-controlled. 28 participants.

Overview

Trial Therapeutic Area
Haematology|Rare Disease
Trial Disease
Hemophilia B
Trial Stage
Phase II/III
Drug Modality
Gene therapy
Orphan Drug
Yes

Key dates

Initial CTIS Submission Date
27-10-2023

Trial design

open-label, none/not specified-controlled Phase II/III trial across 10 sites in Denmark, Sweden, Germany and others.

Open Label
Yes
Comparator
None/Not specified
Target Sample Size
28
Trial Duration For Participant
3650

Eligibility

Recruits 28 No vulnerable population selected; participants are adult male subjects; consent requirement: "Provided written informed consent.".

Vulnerable Population
No vulnerable population selected; participants are adult male subjects; consent requirement: "Provided written informed consent."

Inclusion criteria

  • {"criterion_text":"- Received treatment with CSL222 in Study CSL222_2001 or Study CSL222_3001, and completed participation in Study CSL222_2001 or Study CSL222_3001 or at least 5 years have passed since receiving CSL222.\n- Provided written informed consent.\n- Willing and able to adhere to all protocol requirements."}

Exclusion criteria

  • {"criterion_text":"- There are no exclusion criteria in this study"}

Endpoints

Primary endpoints

  • {"endpoint_text":"- Number of Participants With Serious Adverse Events (SAEs) and AEs of Special Interest (AESIs)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Percentage of Participants with SAEs and AESIs","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Number of SAEs and AESIs","definition_or_measurement_approach":""}

Secondary endpoints

  • {"endpoint_text":"- Annualized Bleeding Rate (ABR)","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Number of Participants With Zero Total, Spontaneous, Joint, and Traumatic Bleeding Episodes","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Endogenous Factor IX (FIX) Activity","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Change from Baseline by Visit in Endogenous FIX Activity","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Annualized Consumption of FIX Replacement Therapy","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Annualized Infusion Rate of FIX Replacement Therapy","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Number of Participants Remaining Free of Continuous FIX Prophylaxis","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Percentage of Participants Remaining Free of Continuous FIX Prophylaxis","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Number of New Target Joints","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Percentage Resolution of Pre-existing Target Joints","definition_or_measurement_approach":""}
  • {"endpoint_text":"- EuroQol-5 Dimensions-5 Levels (EQ-5D-5L) Index Value","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Change From Baseline in EQ-5D-5L Index Value","definition_or_measurement_approach":""}
  • {"endpoint_text":"- EQ-5D VAS Score","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Change From Baseline in EQ-5D VAS Score","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Hemophilia Quality of Life Questionnaire (Hem-A-QoL) Total Score","definition_or_measurement_approach":""}
  • {"endpoint_text":"- Change From Baseline in Hem-A-QoL Total Score","definition_or_measurement_approach":""}

Recruitment

Planned Sample Size
28
Recruitment Window Months
126
Consent Approach
Written informed consent provided by adult participants ("Provided written informed consent."). Subject information and informed consent documents (adult) available for participating countries in multiple languages including English, Danish, Dutch, French and German.

Geography

Total Number Of Sites
10
Total Number Of Participants
28

Denmark

Earliest CTIS Part Ii Submission Date
02-02-2024
Latest Decision Or Authorization Date
18-11-2024
Processing Time Days
290
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Rigshospitalet
Department Name
Department of Hematology
Contact Person Name
Peter Kampmann
Contact Person Email
peter.kampmann@regionh.dk

Sweden

Earliest CTIS Part Ii Submission Date
23-05-2024
Latest Decision Or Authorization Date
18-11-2024
Processing Time Days
179
Number Of Sites
1
Number Of Participants
2

Sites

Site Name
Region Skane Skanes Universitetssjukhus
Department Name
Hematologi, Onkologi och Strålningsfysik
Contact Person Name
Jan Astermark
Contact Person Email
Jan.Astermark@med.lu.se

Germany

Earliest CTIS Part Ii Submission Date
17-05-2024
Latest Decision Or Authorization Date
09-09-2025
Processing Time Days
480
Number Of Sites
1
Number Of Participants
2

Sites

Site Name
Vivantes Netzwerk fuer Gesundheit GmbH
Department Name
Klinikum für Angiologie/Hömostaseologie
Contact Person Name
Robert Klamroth

Netherlands

Earliest CTIS Part Ii Submission Date
09-02-2024
Latest Decision Or Authorization Date
18-08-2025
Processing Time Days
556
Number Of Sites
4
Number Of Participants
12

Sites

Site Name
Universitair Medisch Centrum Utrecht
Department Name
Van Creveldkliniek
Contact Person Name
Paul van der Valk
Contact Person Email
p.r.vandervalk@umcutrecht.nl
Site Name
Academisch Medisch Centrum
Department Name
Internal and Vascular Medicine & Haemophilia
Contact Person Name
Michiel Coppens
Contact Person Email
m.coppens@amsterdamumc.nl
Site Name
Universitair Medisch Centrum Groningen
Department Name
Haematology
Contact Person Name
Karina Meijer
Contact Person Email
k.meijer@umcg.nl
Site Name
Erasmus Universitair Medisch Centrum Rotterdam (Erasmus MC)
Department Name
Haematology
Contact Person Name
Frank Leebeek
Contact Person Email
f.leebeek@erasmusmc.nl

Ireland

Earliest CTIS Part Ii Submission Date
12-06-2024
Latest Decision Or Authorization Date
23-10-2025
Processing Time Days
498
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
St James's Hospital
Department Name
Haematology
Contact Person Name
Niamh O'Connell
Contact Person Email
research@stjames.ie

Belgium

Earliest CTIS Part Ii Submission Date
05-02-2024
Latest Decision Or Authorization Date
01-12-2025
Processing Time Days
665
Number Of Sites
2
Number Of Participants
6

Sites

Site Name
Cliniques Universitaires Saint-Luc
Department Name
Hematology
Contact Person Name
Cedric Hermans
Contact Person Email
cedric.hermans@uclouvain.be
Site Name
UZ Leuven
Department Name
Vascular Medicine
Contact Person Name
Quentin Van Thillo
Contact Person Email
quentin.vanthillo@uzleuven.be

Sponsor

Primary sponsor

Full Name
CSL Behring LLC
Organisation Type
Laboratory/Research/Testing facility
Country Of Registered Address
United States

Contract research organisations

Name
Block Clinical Inc.
Responsibilities
Patient travel and reimbursement
Name
Everest Clinical Research Corporation
Responsibilities
codes: 6,7 (as listed)
Name
Medpace Inc.
Responsibilities
Institutional Review Board (IRB)/Ethics Committee (EC) Management; Site budget and contract negotiation; Investigator Site Payments; other operational duties (codes listed)
Name
Inseption Group LLC
Responsibilities
eTMF management
Name
Precision For Medicine Inc.
Responsibilities
supporting laboratory/diagnostic duties (code: 4)

Third parties

  • {"country":"United States","full_name":"Block Clinical Inc.","duties_or_roles":"Patient travel and reimbursement","organisation_type":"Non-Pharmaceutical company"}
  • {"country":"Denmark","full_name":"Unilabs A/S","duties_or_roles":"code: 4","organisation_type":"Laboratory/Research/Testing facility"}
  • {"country":"Canada","full_name":"Everest Clinical Research Corporation","duties_or_roles":"code: 6; code: 7","organisation_type":"Laboratory/Research/Testing facility"}
  • {"country":"United States","full_name":"Medpace Inc.","duties_or_roles":"codes: 1,12,13,15 (Institutional Review Board (IRB)/Ethics Committee (EC) Management; Site budget and contract negotiation; Investigator Site Payments); code:5; code:8","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Precision For Medicine Inc.","duties_or_roles":"code: 4","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Inseption Group LLC","duties_or_roles":"eTMF management","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Medidata Solutions Inc.","duties_or_roles":"code: 7","organisation_type":"Non-Pharmaceutical company"}
  • {"country":"Belgium","full_name":"MEDPACE LABORATORIES","duties_or_roles":"code: 4","organisation_type":"Laboratory/Research/Testing facility"}
  • {"country":"Germany","full_name":"ProtaGene CGT GmbH","duties_or_roles":"code: 4","organisation_type":"Pharmaceutical company"}
  • {"country":"United States","full_name":"Medpace Reference Laboratories LLC","duties_or_roles":"code: 4","organisation_type":"Laboratory/Research/Testing facility"}

Investigational products

Investigational Product Name
Hemgenix 1 x 10^13 genome copies/mL concentrate for solution for infusion
Active Substance
ETRANACOGENE DEZAPARVOVEC
Modality
Gene therapy
Routes Of Administration
IV INFUSION
Route
IV INFUSION
Authorisation Status
Marketing authorisation referenced (EU/1/22/1715/001), product authorization status code: 2
Orphan Designation
Yes
Maximum Dose
2 millilitre(s)/kilogram

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