Clinical trial • Phase III • Haematology|Rare Disease

ETAVOPIVAT for Sickle cell disease

Phase III trial of ETAVOPIVAT for Sickle cell disease.

Overview

Trial Therapeutic Area
Haematology|Rare Disease
Trial Disease
Sickle cell disease
Trial Stage
Phase III
Drug Modality
Small molecule
Paediatric Trial
Yes
Orphan Drug
Yes

Key dates

Initial CTIS Submission Date
11-11-2024
First CTIS Authorization Date
18-03-2025

Trial design

Randomised, placebo (matching placebo) comparator arm; active investigational product: etavopivat a 200 mg oral tablet (etavopivat a 200 mg).-controlled Phase III trial in Belgium, Italy, Netherlands and others.

Randomised
Yes
Comparator
Placebo (matching placebo) comparator arm; active investigational product: Etavopivat A 200 mg oral tablet (Etavopivat A 200 mg).
Target Sample Size
333

Eligibility

Recruits 333 paediatric patients.

Vulnerable Population
Study includes adolescents (12-17 years). Subject information and informed consent documents for adolescents (12-17 years), parents/guardians and legal authorised representatives (LAR) are included in the application (country-specific PIIC/consent forms listed). Vulnerable-population procedures include parent/guardian/LAR consent materials and adolescent information/assent documents (multiple language versions available).

Inclusion criteria

  • {"criterion_text":"- Male or female\n- Age 12 years or above at the time of signing the informed consent\n- Confirmed diagnosis of sickle cell disease (SCD): Documentation of SCD genotype (HbSS, HbSβ0-thalassemia or other sickle cell syndrome variants) based on prior history of laboratory testing or screening test results from central laboratory.\n- Have 2−15 episodes of documented vaso-occlusive crises (VOCs) within the 12 months prior to screening. Documentation must exist in the participant’s medical record prior to randomisation. Events based solely on participant recall without supporting documentation should not be counted towards eligibility.\n- Hb ≥5.0 and ≤10.0 g/dL (≥50 and ≤100 g/L) at screening."}

Exclusion criteria

  • {"criterion_text":"- Use of voxelotor or similar agent within 28 days prior to starting study treatment or anticipated need for this agent during the study\n- Severe renal dysfunction (estimated glomerular filtration rate [eGFR] at screening, calculated by the central laboratory <30 mL/min/1.73 m2) or on chronic dialysis.\n- Travelled distance on standardized 6-minute walking test below 100m at screening.\n- Use of a selectin antagonist (e.g., crizanlizumab, monoclonal antibody or small molecule) within 28 days or 5 half-lives (whichever is longer) prior to starting study treatment or anticipated need for such agents during the study.\n- Receiving regularly scheduled blood (RBC) transfusion therapy (also termed chronic, prophylactic, or preventive transfusion) or ≥6 transfusion events in the previous 12 months (i.e., an average of 1 transfusion event every 60 days).\n- Participants who have received an RBC transfusion for any reason within 60 days of the screening period or 60 days of the randomisation day are only eligible if HbA (adult Hb) <10% by Hb electrophoresis is documented prior to starting study treatment.\n- Receiving or use of concomitant medications that are strong inducers of CYP3A4 within 2 weeks of starting study treatment or anticipated need for such agents during the study.\n- Use of erythropoietin or other haematopoietic growth factor treatment within 28 days of starting study treatment or anticipated need for such agents during the study.\n- Receipt of prior cellular-based therapy (e.g., haematopoietic cell transplant, gene modification therapy).\n- Hepatic dysfunction characterized by: Alanine aminotransferase (ALT) >4.0 × upper limit of normal (ULN) or Direct bilirubin >3.0 × ULN.\n- Participants who are not taking or are unable to take antimalarial prophylaxis at the time of consent and during the study if they live in areas of endemic malaria where prophylaxis is recommended."}

Endpoints

Primary endpoints

  • {"endpoint_text":"- Number of adjudicated VOC events with a medical contact.","definition_or_measurement_approach":"Count of adjudicated vaso-occlusive crisis (VOC) events with a medical contact (as written in the primary endpoint)."}

Secondary endpoints

  • {"endpoint_text":"- Change in Hb >1 g/dL (yes/no)","definition_or_measurement_approach":"Binary assessment of whether haemoglobin change is greater than 1 g/dL."}
  • {"endpoint_text":"- Time to onset of first adjudicated VOC.","definition_or_measurement_approach":"Time-to-event measurement from randomisation to first adjudicated VOC."}
  • {"endpoint_text":"- Change in standardised T-score on the PROMIS Fatigue 7a Scale.","definition_or_measurement_approach":"Change in PROMIS Fatigue 7a T-score from baseline to assessment timepoint."}
  • {"endpoint_text":"- Change in haemoglobin (Hb)","definition_or_measurement_approach":"Continuous change in haemoglobin concentration from baseline."}
  • {"endpoint_text":"- Change in lactate dehydrogenase (LDH)","definition_or_measurement_approach":"Change in LDH from baseline (laboratory measurement)."}
  • {"endpoint_text":"- Change in absolute reticulocyte count","definition_or_measurement_approach":"Change in absolute reticulocyte count from baseline (laboratory measurement)."}
  • {"endpoint_text":"- Change in indirect bilirubin","definition_or_measurement_approach":"Change in indirect bilirubin from baseline (laboratory measurement)."}
  • {"endpoint_text":"- Change in distance travelled during the 6-minute walking test (6MWT)","definition_or_measurement_approach":"Change in 6MWT distance (meters) from baseline."}
  • {"endpoint_text":"- Participants achieving the threshold for clinically meaningful change (yes/no) in PROMIS fatigue scale 7a","definition_or_measurement_approach":"Proportion achieving predefined clinically meaningful change threshold on PROMIS Fatigue 7a (yes/no)."}
  • {"endpoint_text":"- Participants achieving the threshold for clinically meaningful change (yes/no) in 6MWT","definition_or_measurement_approach":"Proportion achieving predefined clinically meaningful change threshold on 6MWT (yes/no)."}

Recruitment

Planned Sample Size
333
Recruitment Window Months
45
Consent Approach
Adults provide informed consent. Adolescents (12-17) have age-specific participant information and consent/assent forms; parent/guardian and legal authorised representative (LAR) consent forms are provided. Multiple country/language PIIC documents are included (English, French, Dutch, Italian, Spanish, Greek as per submitted subject information and consent form documents).

Geography

Total Number Of Sites
36
Total Number Of Participants
75

Belgium

Earliest CTIS Part Ii Submission Date
06-03-2025
Latest Decision Or Authorization Date
18-09-2025
Processing Time Days
196
Number Of Sites
6
Number Of Participants
10

Sites

Site Name
Association Hospitaliere De Bruxelles Hopital Universitaire Des Enfants Reine Fabiola
Principal Investigator Name
Laurence Dedeken
Principal Investigator Email
laurence.dedeken@hubruxelles.be
Contact Person Name
Laurence Dedeken
Site Name
Hopital Erasme
Principal Investigator Name
Martin Colard
Principal Investigator Email
martin.colard@hubruxelles.be
Contact Person Name
Martin Colard
Contact Person Email
martin.colard@hubruxelles.be
Site Name
Universitair Ziekenhuis Antwerpen
Principal Investigator Name
Philip Maes
Principal Investigator Email
philip.maes@uza.be
Contact Person Name
Philip Maes
Contact Person Email
philip.maes@uza.be
Site Name
Antwerp University Hospital
Principal Investigator Name
Ann Van De Velde
Principal Investigator Email
ann.vandevelde@uza.be
Contact Person Name
Ann Van De Velde
Contact Person Email
ann.vandevelde@uza.be
Site Name
UZ Leuven
Principal Investigator Name
Veerle Labarque
Principal Investigator Email
veerle.labarque@uzleuven.be
Contact Person Name
Veerle Labarque
Contact Person Email
veerle.labarque@uzleuven.be
Site Name
CHU Saint Pierre
Principal Investigator Name
Anna Vanderfaeillie
Principal Investigator Email
anna.vanderfaeillie@stpierre-bru.be
Contact Person Name
Anna Vanderfaeillie

Italy

Earliest CTIS Part Ii Submission Date
24-02-2025
Latest Decision Or Authorization Date
19-09-2025
Processing Time Days
207
Number Of Sites
9
Number Of Participants
20

Sites

Site Name
Azienda Ospedaliero-Universitaria San Luigi Gonzaga
Principal Investigator Name
Vincenzo Voi
Principal Investigator Email
vincenzo.voi@unito.it
Contact Person Name
Vincenzo Voi
Contact Person Email
vincenzo.voi@unito.it
Site Name
Azienda Socio Sanitaria Territoriale Degli Spedali Civili Di Brescia
Principal Investigator Name
Elisa Bertoni
Principal Investigator Email
elisa.bertoni@asst-spedalicivili.it
Contact Person Name
Elisa Bertoni
Site Name
Azienda Ospedaliera Ospedali Riuniti Villa Sofia Cervello
Principal Investigator Name
Rosario Di Maggio
Principal Investigator Email
rdm83@hotmail.it
Contact Person Name
Rosario Di Maggio
Contact Person Email
rdm83@hotmail.it
Site Name
Fondazione IRCCS San Gerardo Dei Tintori
Principal Investigator Name
Paola Consuelo Corti
Principal Investigator Email
paolaconsuelo.corti@irccs-sangerardo.it
Contact Person Name
Paola Consuelo Corti
Site Name
Centro Ricerche Cliniche Di Verona S.r.l.
Principal Investigator Name
Lucia De Franceschi
Principal Investigator Email
lucia.defranceschi@univr.it
Contact Person Name
Lucia De Franceschi
Contact Person Email
lucia.defranceschi@univr.it
Site Name
ARNAS Garibaldi Di Catania
Principal Investigator Name
Roberto Lisi
Principal Investigator Email
talassemia@ao-garibaldi.ct.it
Contact Person Name
Roberto Lisi
Contact Person Email
talassemia@ao-garibaldi.ct.it
Site Name
Azienda Ospedaliero Universitaria Di Modena
Principal Investigator Name
Giovanni Palazzi
Principal Investigator Email
palazzi.giovanni@aou.mo.it
Contact Person Name
Giovanni Palazzi
Contact Person Email
palazzi.giovanni@aou.mo.it
Site Name
Azienda Ospedaliera Universita' Degli Studi Della Campania Luigi Vanvitelli
Principal Investigator Name
Maddalena Casale
Principal Investigator Email
maddalena.casale@unicampania.it
Contact Person Name
Maddalena Casale
Site Name
Azienda Ospedaliera di Padova
Principal Investigator Name
Raffaella Colombatti
Principal Investigator Email
raffaella.colombatti@unipd.it
Contact Person Name
Raffaella Colombatti
Contact Person Email
raffaella.colombatti@unipd.it

Netherlands

Earliest CTIS Part Ii Submission Date
24-02-2025
Latest Decision Or Authorization Date
17-09-2025
Processing Time Days
205
Number Of Sites
4
Number Of Participants
10

Sites

Site Name
Erasmus Universitair Medisch Centrum Rotterdam (Erasmus MC)
Principal Investigator Name
Anita Rijneveld
Principal Investigator Email
a.rijneveld@erasmusmc.nl
Contact Person Name
Anita Rijneveld
Contact Person Email
a.rijneveld@erasmusmc.nl
Site Name
Amsterdam UMC Stichting
Principal Investigator Name
Bart Biemond
Principal Investigator Email
hematology@amsterdamumc.nl
Contact Person Name
Bart Biemond
Contact Person Email
hematology@amsterdamumc.nl
Site Name
Universitair Medisch Centrum Utrecht
Principal Investigator Name
E.J. Van Beers
Principal Investigator Email
e.j.vanbeers-3@umcutrecht.nl
Contact Person Name
E.J. Van Beers
Contact Person Email
e.j.vanbeers-3@umcutrecht.nl
Site Name
Haga Hospital
Principal Investigator Name
Jean Louis Kerkhoffs
Principal Investigator Email
j.kerkhoffs@hagaziekenhuis.nl
Contact Person Name
Jean Louis Kerkhoffs
Contact Person Email
j.kerkhoffs@hagaziekenhuis.nl

Greece

Earliest CTIS Part Ii Submission Date
17-01-2025
Latest Decision Or Authorization Date
19-09-2025
Processing Time Days
245
Number Of Sites
5
Number Of Participants
15

Sites

Site Name
University General Hospital Of Ioannina
Department Name
Department of Hematology
Principal Investigator Name
Eleni Kapsali
Principal Investigator Email
elkapsali@gmail.com
Contact Person Name
Eleni Kapsali
Contact Person Email
elkapsali@gmail.com
Site Name
University General Hospital Of Thessaloniki Ahepa
Department Name
Thalassemia Unit, 1st Department of Internal Medicine
Principal Investigator Name
Despoina Pantelidou
Principal Investigator Email
dpantelidou@yahoo.gr
Contact Person Name
Despoina Pantelidou
Contact Person Email
dpantelidou@yahoo.gr
Site Name
Hippokration Hospital
Department Name
Thalassemia and Sickle Cell Unit
Principal Investigator Name
Sophia Delicou
Principal Investigator Email
sophiadelicou@gmail.com
Contact Person Name
Sophia Delicou
Contact Person Email
sophiadelicou@gmail.com
Site Name
Laiko General Hospital Of Athens
Department Name
Thalassemia Unit, Center of Expertise in Hemoglobinopathies
Principal Investigator Name
Maria Dimopoulou
Principal Investigator Email
mdimkma@gmail.com
Contact Person Name
Maria Dimopoulou
Contact Person Email
mdimkma@gmail.com
Site Name
Nosokomeio Paidon I Agia Sofia
Department Name
Thalassemia Unit, First Department of Pediatrics
Principal Investigator Name
Antonis Kattamis
Principal Investigator Email
ankatt@med.uoa.gr
Contact Person Name
Antonis Kattamis
Contact Person Email
ankatt@med.uoa.gr

France

Earliest CTIS Part Ii Submission Date
18-02-2025
Latest Decision Or Authorization Date
24-09-2025
Processing Time Days
218
Number Of Sites
8
Number Of Participants
12

Sites

Site Name
Centre Hospitalier Universitaire De Bordeaux
Principal Investigator Name
Arnaud Desclaux
Principal Investigator Email
arnaud.desclaux@chu-bordeaux.fr
Contact Person Name
Arnaud Desclaux
Site Name
Centre Hospitalier Universitaire Grenoble Alpes
Principal Investigator Name
Caroline Makowski
Principal Investigator Email
cmakowski@chu-grenoble.fr
Contact Person Name
Caroline Makowski
Contact Person Email
cmakowski@chu-grenoble.fr
Site Name
Assistance Publique Hopitaux De Paris (Paris site)
Principal Investigator Name
Laure Joseph
Principal Investigator Email
laure.joseph@aphp.fr
Contact Person Name
Laure Joseph
Contact Person Email
laure.joseph@aphp.fr
Site Name
Hospices Civils De Lyon
Principal Investigator Name
Giovanna Cannas
Principal Investigator Email
giovanna.cannas@chu-lyon.fr
Contact Person Name
Giovanna Cannas
Contact Person Email
giovanna.cannas@chu-lyon.fr
Site Name
Assistance Publique Hopitaux De Paris (Boulevard Serurier site)
Principal Investigator Name
Valentine Brousse
Principal Investigator Email
valentine.brousse@aphp.fr
Contact Person Name
Valentine Brousse
Contact Person Email
valentine.brousse@aphp.fr
Site Name
Assistance Publique Hopitaux De Paris (Creteil site)
Principal Investigator Name
Pablo Bartolucci
Principal Investigator Email
pablo.bartolucci@aphp.fr
Contact Person Name
Pablo Bartolucci
Contact Person Email
pablo.bartolucci@aphp.fr
Site Name
Assistance Publique Hopitaux De Paris (Bobigny site)
Principal Investigator Name
Sylvain Le Jeune
Principal Investigator Email
sylvain.le-jeune@aphp.fr
Contact Person Name
Sylvain Le Jeune
Contact Person Email
sylvain.le-jeune@aphp.fr
Site Name
Centre Hospitalier Universitaire Rouen
Principal Investigator Name
Cécile Dumesnil De Maricourt
Principal Investigator Email
Cecile.Dumesnil@chu-rouen.fr
Contact Person Name
Cécile Dumesnil De Maricourt
Contact Person Email
Cecile.Dumesnil@chu-rouen.fr

Spain

Earliest CTIS Part Ii Submission Date
30-01-2025
Latest Decision Or Authorization Date
28-01-2026
Processing Time Days
363
Number Of Sites
4
Number Of Participants
8

Sites

Site Name
Hospital Universitario La Paz
Principal Investigator Name
Ana Mendoza
Principal Investigator Email
amendozam.externo@salud.madrid.org
Contact Person Name
Ana Mendoza
Site Name
University Hospital Virgen Del Rocio S.L.
Principal Investigator Name
Salvador Payan Pernia
Principal Investigator Email
salvador.payan.sspa@juntadeandalucia.es
Contact Person Name
Salvador Payan Pernia
Site Name
Hospital General Universitario Gregorio Maranon
Principal Investigator Name
Elena Cela de Julian
Principal Investigator Email
elena.cela@salud.madrid.org
Contact Person Name
Elena Cela de Julian
Contact Person Email
elena.cela@salud.madrid.org
Site Name
Fundacio Hospital Universitari Vall D’Hebron Institut De Recerca
Principal Investigator Name
David Beneitez Pastor
Principal Investigator Email
david.beneitez@vallhebron.cat
Contact Person Name
David Beneitez Pastor
Contact Person Email
david.beneitez@vallhebron.cat

Sponsor

Primary sponsor

Full Name
Novo Nordisk A/S
Organisation Type
Pharmaceutical company
Country Of Registered Address
Denmark

Contract research organisations

Name
IQVIA Limited
Responsibilities
Central Laboratory, Feasibility Consulting Services
Name
Icon Clinical Research Limited
Responsibilities
Event Adjudication Services
Name
4G Clinical B.V.
Responsibilities
RTSM supplier and RTSM helpdesk
Name
Signant Health Management Limited
Responsibilities
eCOA
Name
Oracle Corporation UK Limited
Responsibilities
CRF supplier

Third parties

  • {"country":"Greece","full_name":"Affidea Piraeus Biopathological","duties_or_roles":"Hospital/Clinic/Other health care facility (local laboratory contact listed)","organisation_type":"Hospital/Clinic/Other health care facility"}
  • {"country":"United Kingdom","full_name":"IQVIA Limited","duties_or_roles":"Central Laboratory, Feasibility Consulting Services","organisation_type":"Pharmaceutical company"}
  • {"country":"United Kingdom","full_name":"Oracle Corporation UK Limited","duties_or_roles":"CRF supplier","organisation_type":"Pharmaceutical company"}
  • {"country":"Ireland","full_name":"Icon Clinical Research Limited","duties_or_roles":"Event Adjudication Services","organisation_type":"Pharmaceutical company"}
  • {"country":"Netherlands","full_name":"4G Clinical B.V.","duties_or_roles":"RTSM supplier and RTSM helpdesk","organisation_type":"Non-Pharmaceutical company"}
  • {"country":"United Kingdom","full_name":"Signant Health Management Limited","duties_or_roles":"eCOA","organisation_type":"Pharmaceutical company"}

Investigational products

Investigational Product Name
Etavopivat A 200 mg
Active Substance
ETAVOPIVAT
Modality
Small molecule
Routes Of Administration
ORAL
Route
Oral
Authorisation Status
Unauthorized (investigational product in this trial)
Orphan Designation
Yes
Starting Dose
200 mg
Dose Levels
200 mg
Investigational Product Name
Placebo
Modality
Other
Authorisation Status
Not applicable

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