Clinical trial • Phase III • Haematology | Rare Disease

BEROTRALSTAT for Hereditary angioedema

Phase III trial of BEROTRALSTAT for Hereditary angioedema. open-label. 79 participants.

Overview

Trial Therapeutic Area
Haematology | Rare Disease
Trial Disease
Hereditary angioedema
Trial Stage
Phase III
Drug Modality
Small molecule
Paediatric Trial
Yes

Key dates

Initial CTIS Submission Date
16-05-2024
First CTIS Authorization Date
17-07-2024

Trial design

open-label Phase III trial in Czechia, Poland, Slovakia and others.

Open Label
Yes
Target Sample Size
79

Eligibility

Recruits 79 paediatric patients.

Pregnancy Exclusion
Pregnancy or breastfeeding
Vulnerable Population
Participant or parent/ legally designated representative (for participants < 18 years of age) able to provide written informed consent. For participants < 18 years of age, based on the child’s age and local regulatory requirements, participant assent will be collected as appropriate.

Inclusion criteria

  • {"criterion_text":"- Males and non-pregnant, non-lactating females who are currently enrolled as a subject or were previously enrolled and did not discontinue due to an adverse event or due to noncompliance in BioCryst-sponsored Study 302, 204, or 304."}
  • {"criterion_text":"- Participant or parent/ legally designated representative (for participants < 18 years of age) able to provide written informed consent. For participants < 18 years of age, based on the child’s age and local regulatory requirements, participant assent will be collected as appropriate."}
  • {"criterion_text":"- Would benefit from continued berotralstat treatment in the opinion of the investigator"}
  • {"criterion_text":"- Female subjects must meet at least 1 of the following requirements: a. Be a WOCBP (defined as a female following menarche and prior to becoming post-menopausal who has not had a hysterectomy or bilateral salpingectomy and bilateral oophorectomy) who agrees to use at least an acceptable effective contraceptive method during the study. b. Be a woman of nonchildbearing potential (defined as postmenopausal [no menses for at least 12 months without an alternative medical cause] or has had a hysterectomy or a bilateral salpingectomy and bilateral oophorectomy)."}
  • {"criterion_text":"- In the opinion of the investigator, the subject is expected to adequately comply with all required study procedures"}

Exclusion criteria

  • {"criterion_text":"- Any condition or situation, including medical history or changes in medical history, which, in the opinion of the investigator or sponsor, would interfere with the subject's safety or ability to participate in the study"}
  • {"criterion_text":"- Dementia, altered mental status, or any psychiatric condition that would prohibit the understanding or rendering of informed consent."}
  • {"criterion_text":"- Hypersensitivity to the active substance or to any of the excipients in the IMP"}
  • {"criterion_text":"- Use of other medications for long-term prophylaxis of HAE attacks at the Baseline visit or any time during the study. These include: C1-INH, tranexamic acid, androgens, or lanadelumab"}
  • {"criterion_text":"- Use of any other investigational medicinal product at the Baseline visit or any time during the study."}
  • {"criterion_text":"- Pregnancy or breastfeeding"}
  • {"criterion_text":"- Subjects with an immediate family relationship to either sponsor employees, the investigator, or employees of the study site who are named on the delegation log."}
  • {"criterion_text":"- Subjects who are held in an institution by a governmental or judicial order."}

Endpoints

Primary endpoints

  • {"endpoint_text":"- Number and proportion of subjects with a treatment-related TEAE\n- Number and proportion of subjects who experience a serious adverse event (SAE)\n- Number and proportion of subjects who experience a treatment-related Grade 3 or 4 TEAE\n- Number and proportion of subjects who experience a treatment-related Grade 3 or 4 treatment-emergent chemistry abnormality\n- Number and proportion of subjects who discontinue due to a TEAE","definition_or_measurement_approach":"Primary endpoints are safety outcome counts and proportions (number and proportion of subjects meeting each listed safety outcome as recorded during study treatment/safety reporting)."}

Secondary endpoints

  • {"endpoint_text":"- Another mechanism is available to provide drug to the subject(eg, market access), or until the sponsor discontinues all global commercialization and development of berotralstat for the prevention of angioedema attacks, whichever comes first","definition_or_measurement_approach":"Time/condition-based endpoint: study treatment continued until an alternative access mechanism is available or until sponsor discontinues global development/commercialization for HAE prevention, whichever occurs first."}

Recruitment

Planned Sample Size
79
Recruitment Window Months
124
Consent Approach
Participant or parent/ legally designated representative (for participants < 18 years of age) able to provide written informed consent. For participants < 18 years of age, based on the child’s age and local regulatory requirements, participant assent will be collected as appropriate. Country- and age-specific subject information and informed consent/assent documents are provided (examples in the submitted documents include Czech, Slovak, Polish, Spanish, French, Italian and English versions and specific adolescent/assent ICFs).

Geography

Total Number Of Sites
9
Total Number Of Participants
45

Czechia

Earliest CTIS Part Ii Submission Date
17-07-2024
Latest Decision Or Authorization Date
05-06-2025
Processing Time Days
323
Number Of Sites
2
Number Of Participants
6

Sites

Site Name
Fakultni Nemocnice U Sv Anny V Brne
Department Name
Ustav klinicke imunologie a alergologie
Principal Investigator Name
Roman Hakl
Principal Investigator Email
roman.hakl@fnusa.cz
Contact Person Name
Roman Hakl
Contact Person Email
roman.hakl@fnusa.cz
Site Name
Fakultni Nemocnice Plzen
Department Name
Oddělení klinické Alergologie a Imunologie
Principal Investigator Name
Martina Vachová
Principal Investigator Email
vachovam@fnplzen.cz
Contact Person Name
Martina Vachová
Contact Person Email
vachovam@fnplzen.cz

Poland

Earliest CTIS Part Ii Submission Date
17-07-2024
Latest Decision Or Authorization Date
18-03-2026
Processing Time Days
609
Number Of Sites
1
Number Of Participants
13

Sites

Site Name
Samodzielny Publiczny Zaklad Opieki Zdrowotnej Szpital Uniwersytecki W Krakowie
Department Name
Centrum alergologii
Principal Investigator Name
Marcin Stobiecki
Principal Investigator Email
marcin.stobiecki@uj.edu.pl
Contact Person Name
Marcin Stobiecki
Contact Person Email
marcin.stobiecki@uj.edu.pl

Slovakia

Earliest CTIS Part Ii Submission Date
19-07-2024
Latest Decision Or Authorization Date
10-06-2025
Processing Time Days
326
Number Of Sites
1
Number Of Participants
12

Sites

Site Name
Univerzitna Nemocnica Martin
Department Name
Centrum pre hereditarny angioedem
Principal Investigator Name
Milos Jesenak
Principal Investigator Email
sekrlps@unm.sk
Contact Person Name
Milos Jesenak
Contact Person Email
sekrlps@unm.sk

Spain

Earliest CTIS Part Ii Submission Date
16-09-2025
Latest Decision Or Authorization Date
16-09-2025
Number Of Sites
1
Number Of Participants
1

Sites

Site Name
Hospital Universitario La Paz
Department Name
Allergy (Paediatric)
Principal Investigator Name
Elsa Phillips
Principal Investigator Email
elsa.phillips@salud.madrid.org
Contact Person Name
Elsa Phillips
Contact Person Email
elsa.phillips@salud.madrid.org

Italy

Earliest CTIS Part Ii Submission Date
22-10-2025
Latest Decision Or Authorization Date
18-03-2026
Processing Time Days
147
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Azienda Ospedaliera di Padova
Department Name
UOSD Allergologia
Principal Investigator Name
Riccardo Senter
Principal Investigator Email
riccardo.senter@aopd.veneto.it
Contact Person Name
Riccardo Senter
Contact Person Email
riccardo.senter@aopd.veneto.it

Germany

Earliest CTIS Part Ii Submission Date
01-09-2025
Latest Decision Or Authorization Date
18-03-2026
Processing Time Days
198
Number Of Sites
1
Number Of Participants
3

Sites

Site Name
Goethe University Frankfurt
Department Name
Interdisciplinary Comprehensive Care Centre for Hereditary Angioedema
Principal Investigator Name
Emel Aygören-Pürsün
Principal Investigator Email
aygoeren@em.uni-frankfurt.de
Contact Person Name
Emel Aygören-Pürsün
Contact Person Email
aygoeren@em.uni-frankfurt.de

France

Earliest CTIS Part Ii Submission Date
04-09-2025
Latest Decision Or Authorization Date
18-03-2026
Processing Time Days
195
Number Of Sites
2
Number Of Participants
7

Sites

Site Name
Trousseau Hospital
Department Name
Allergology
Principal Investigator Name
Melisande Bourgoin-heck
Principal Investigator Email
elisande.bourgoing-heck@aphp.fr
Contact Person Name
Melisande Bourgoin-heck
Site Name
Centre Hospitalier Universitaire Grenoble Alpes
Department Name
Paediatric immuno-haemato-oncology
Principal Investigator Name
Anne Pagnier
Principal Investigator Email
APagnier@chu-grenoble.fr
Contact Person Name
Anne Pagnier
Contact Person Email
APagnier@chu-grenoble.fr

Sponsor

Primary sponsor

Full Name
Biocryst Pharmaceuticals Inc.
Organisation Type
Pharmaceutical company
Country Of Registered Address
United States

Contract research organisations

Name
Pharpoint Research Inc.
Responsibilities
Sponsor duties codes: [10, 6, 7]
Name
AMS Advanced Medical Services Limited
Responsibilities
Sponsor duties codes: [1, 12]

Third parties

  • {"country":"United States","full_name":"Pharpoint Research Inc.","duties_or_roles":"sponsorDuties codes: [10, 6, 7] (as recorded in CTIS third party entry)","organisation_type":"Pharmaceutical company"}
  • {"country":"United Kingdom","full_name":"AMS Advanced Medical Services Limited","duties_or_roles":"sponsorDuties codes: [1, 12] (as recorded in CTIS third party entry)","organisation_type":"Pharmaceutical company"}

Investigational products

Investigational Product Name
Berotralstat / BEROTRALSTAT
Active Substance
BEROTRALSTAT
Modality
Small molecule
Routes Of Administration
Oral
Route
Oral
Authorisation Status
Investigational medicinal product (IMP); MIA number reported for IMP11566/00001 (as recorded)
Dose Levels
Reported max daily dose amounts in submission: 150 mg; 108 mg; 96 mg; 78 mg; 66 mg
Maximum Dose
150 mg

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